Amish, Mennonite, and Hutterite
Genetic Disorder Database

Short stature, auditory canal atresia, mandibular hypoplasia, skeletal abnormalities

Disorder
OMIM #: #602471  (Click to access OMIM database)
Disorder: Short stature, auditory canal atresia, mandibular hypoplasia, skeletal abnormalities 
Also known as: SAMS 
Clinical
Phenotype: short stature, external auditory canal atresia, mandibular hypoplasia, skeletal defects, ossification abnormalities, feeding difficulties, respiratory tract infections, hypotelorism, slanted palpebral fissures, micrognathia, contractures, hearing impairment 
Seen In: Amish
Old Order Mennonite
Old Colony Mennonite
Unknown/Other Mennonite
Hutterite
Remarks: Autosomal recessive 
Mutations
1   Old Colony Mennonite  
Gene: GSC
Base Change: C>T, at nucleotide 400
Amino Acid Change: gln 134 --> term
Last updated: 2023-02-02 

References
Lemire EG, Hildes-Ripstein GE, Reed MH, Chudley AE. (1998) SAMS: provisionally unique multiple congenital anomalies syndrome consisting of short stature, auditory canal atresia, mandibular hypoplasia, and skeletal abnormalities. Am J Med Genet Jan 23;75(3):256-60.
PubMed ID: 9475592 
Parry DA, Logan CV, Stegmann AP, Abdelhamed ZA, Calder A, Khan S, Bonthron DT, Clowes V, Sheridan E, Ghali N, Chudley AE, Dobbie A, Stumpel CT, Johnson CA. (2013) SAMS, a syndrome of short stature, auditory-canal atresia, mandibular hypoplasia, and skeletal abnormalities is a unique neurocristopathy caused by mutations in Goosecoid. Am J Hum Genet Dec 5;93(6):1135-42.
PubMed ID: 24290375 

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