Amish, Mennonite, and Hutterite
Genetic Disorder Database

Mitochondrial DNA depletion syndrome 3 (hepatocerebral form)

Disorder
OMIM #: #251880  (Click to access OMIM database)
Disorder: Mitochondrial DNA depletion syndrome 3 (hepatocerebral form) 
Also known as: MTDPS3 
Clinical
Phenotype: hyperreflexia, irritability, hypotonia, cystathioninuria, hepatomegaly, depletion of mtDNA in liver tissue, liver fibrosis, cholestasis, cirrhosis, demylelination, death by 12 months of age from liver disease 
Seen In: Amish
Old Order Mennonite
Old Colony Mennonite
Unknown/Other Mennonite
Hutterite
Remarks:

Testing is available at LHSC.

Autosomal recessive 

Mutations
1   Old Colony Mennonite  
Gene: DGUOK
Base Change: G>T, at nucleotide 763
Amino Acid Change: asp 255 --> tyr
Last updated: 2024-09-24 

References
Tadiboyina V, Rupar A, Atkison P, Feigenbaum A, Kronick J, Wang J, and Hegele R. (2005) Novel Mutation in DGUOK in Hepatocerebral Mitochondrial DNA Depletion Syndrome Associated with Cystathioninurea. Am J Hum Genet 135A: 289-291.
PubMed ID: 15887277 

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