Amish, Mennonite, and Hutterite
Genetic Disorder Database

Autoimmune disease, multisystem, with facial dysmorphism

Disorder
OMIM #: #613385  (Click to access OMIM database)
Disorder: Autoimmune disease, multisystem, with facial dysmorphism 
Also known as: ADMFD
ITCH deficiency 
Clinical
Phenotype: short stature, hepatomegaly, developmental delay, splenomegaly, hypotonia, severe combined immunodeficiency, macrocephaly, frontal bossing, midfacial hypoplasia, prominent occiput, micrognathia, low-set ears, proptosis, chronic lung disease 
Seen In: Amish
Old Order Mennonite
Old Colony Mennonite
Unknown/Other Mennonite
Hutterite
Remarks:  
Mutations
1   Amish  
Gene: ITCH
Base Change: c.394dupA
Amino Acid Change: p.Ile132Asnfs*9
Last updated: 2023-02-01 

References
Lohr NJ, Molleston JP, Strauss KA, Torres-Martinez W, Sherman EA, Squires RH, Rider NL, Chikwava KR, Cummings OW, Morton DH, Puffenberger EG. (2010) Human ITCH E3 ubiquitin ligase deficiency causes syndromic multisystem autoimmune disease. Am J Hum Genet 86(3):447-53.
PubMed ID: 20170897 
Wolfe R, Heiman P, D'Annibale O, Karunanidhi A, Powers A, Mcguire M, Seminotti B, Dobrowolski SF, Reyes-Múgica M, Torok KS, Mohsen AW, Vockley J, Ghaloul-Gonzalez L. (2022) ITCH deficiency clinical phenotype expansion and mitochondrial dysfunction. Mol Genet Metab Rep Oct 29;33:100932.
PubMed ID: 36338154 

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